EJMCR. 2020; 4(2): 60-64

Littoral cell angioma of the spleen in a patient with cerebral palsy and sigmoid volvulus: a rare case report

Authors: Salim Gumus, Burak Uz, Faruk Saltabas.

ABSTRACT

Background: Littoral cell angioma (LCA) is a rare vascular tumour of the spleen with unique histologic and immunophenotypic features. LCA is generally diagnosed incidentally and has a benign clinical course. However, it has rarely been reported to behave as a malign entity. Case presentation: A 49-year-old woman with cerebral palsy admitted to the hospital suffering from abdominal pain and weight loss. Laboratory results revealed iron deficiency anaemia and mild thrombocytopenia. Computed tomography scan revealed splenomegaly with multiple hypoattenuating lesions. A diagnostic and therapeutic open splenectomy and sigmoid colectomy were performed to exclude possible lymphoproliferative disorders or malignant lesions. The histologic and immunohistochemical studies confirmed the diagnosis of LCA and sigmoid volvulus. The post-operative period was uneventful with a significant increase in haemoglobin and platelet levels. Unfortunately, the patient died due to sepsis 36 days after surgery. Conclusion: This is the first case of LCA and sigmoid volvulus. Although this association is likely to be entirely coincidental, clinicians should be aware of this rare clinicopathologic entity whilst evaluating the differential diagnosis of splenomegaly with solitary or multiple nodules.

Keywords:
Littoral cell angioma, spleen, vascular tumour, cerebral palsy, sigmoid volvulus, case report


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Littoral cell angioma of the spleen in a patient with cerebral palsy and sigmoid volvulus: a rare case report


Authors
Salim Gumus
Department of General Surgery, Medicana International Samsun Hospital, Samsun, Turkey
PubMed articlesGoogle scholar articles

Burak Uz
Burak Uz, Department of Hematology, Medicana International Samsun Hospital, Samsun, Turkey
PubMed articlesGoogle scholar articles

Faruk Saltabas
Faruk Saltabas, Department of Pathology, Medicana International Samsun Hospital, Samsun, Turkey
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Correspondence to:
. Burak Uz, Internal Medicine and Hematology, Medicana International Samsun Hospital, Samsun, Turkey.; burakuz78@gmail.com

Publication history
Received 01 Jun 2019
Revised 06 Dec 2019
Accepted 17 Feb 2020
Published online 25 Feb 2020
Published in print 12 Mar 2020

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Pubmed Style

Gumus S, Uz B, Saltabas F. Littoral cell angioma of the spleen in a patient with cerebral palsy and sigmoid volvulus: a rare case report. EJMCR. 2020; 4(2): 60-64. doi:10.24911/ejmcr/173-1559125473


Web Style

Gumus S, Uz B, Saltabas F. Littoral cell angioma of the spleen in a patient with cerebral palsy and sigmoid volvulus: a rare case report. https://www.ejmcr.com/?mno=51087 [Access: March 30, 2020]. doi:10.24911/ejmcr/173-1559125473


AMA (American Medical Association) Style

Gumus S, Uz B, Saltabas F. Littoral cell angioma of the spleen in a patient with cerebral palsy and sigmoid volvulus: a rare case report. EJMCR. 2020; 4(2): 60-64. doi:10.24911/ejmcr/173-1559125473


Vancouver/ICMJE Style

Gumus S, Uz B, Saltabas F. Littoral cell angioma of the spleen in a patient with cerebral palsy and sigmoid volvulus: a rare case report. EJMCR. (2020), [cited March 30, 2020]; 4(2): 60-64. doi:10.24911/ejmcr/173-1559125473


Harvard Style

Gumus, S., Uz, . B. & Saltabas, . F. (2020) Littoral cell angioma of the spleen in a patient with cerebral palsy and sigmoid volvulus: a rare case report. EJMCR, 4 (2), 60-64. doi:10.24911/ejmcr/173-1559125473


Turabian Style

Gumus, Salim, Burak Uz, and Faruk Saltabas. 2020. Littoral cell angioma of the spleen in a patient with cerebral palsy and sigmoid volvulus: a rare case report. European Journal of Medical Case Reports, 4 (2), 60-64. doi:10.24911/ejmcr/173-1559125473


Chicago Style

Gumus, Salim, Burak Uz, and Faruk Saltabas. "Littoral cell angioma of the spleen in a patient with cerebral palsy and sigmoid volvulus: a rare case report." European Journal of Medical Case Reports 4 (2020), 60-64. doi:10.24911/ejmcr/173-1559125473


MLA (The Modern Language Association) Style

Gumus, Salim, Burak Uz, and Faruk Saltabas. "Littoral cell angioma of the spleen in a patient with cerebral palsy and sigmoid volvulus: a rare case report." European Journal of Medical Case Reports 4.2 (2020), 60-64. Print. doi:10.24911/ejmcr/173-1559125473


APA (American Psychological Association) Style

Gumus, S., Uz, . B. & Saltabas, . F. (2020) Littoral cell angioma of the spleen in a patient with cerebral palsy and sigmoid volvulus: a rare case report. European Journal of Medical Case Reports, 4 (2), 60-64. doi:10.24911/ejmcr/173-1559125473


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