EJMCR |

Case Report

Volume: 4 | Issue: 2 | Published: Feb 25, 2020 | Pages: 60 - 64 | DOI: 10.24911/ejmcr/173-1559125473

Littoral cell angioma of the spleen in a patient with cerebral palsy and sigmoid volvulus: a rare case report

Authors: Salim Gumus , Burak Uz , Faruk Saltabas

Article Info

Authors

Salim Gumus

Department of General Surgery, Medicana International Samsun Hospital, Samsun, Turkey

Burak Uz

Burak Uz, Department of Hematology, Medicana International Samsun Hospital, Samsun, Turkey

Faruk Saltabas

Faruk Saltabas, Department of Pathology, Medicana International Samsun Hospital, Samsun, Turkey

Publication History

Received: June 01, 2019

Revised: December 06, 2019

Accepted: February 17, 2020

Published: February 25, 2020

Abstract

Background: Littoral cell angioma (LCA) is a rare vascular tumour of the spleen with unique histologic and immunophenotypic features. LCA is generally diagnosed incidentally and has a benign clinical course. However, it has rarely been reported to behave as a malign entity. Case presentation: A 49-year-old woman with cerebral palsy admitted to the hospital suffering from abdominal pain and weight loss. Laboratory results revealed iron deficiency anaemia and mild thrombocytopenia. Computed tomography scan revealed splenomegaly with multiple hypoattenuating lesions. A diagnostic and therapeutic open splenectomy and sigmoid colectomy were performed to exclude possible lymphoproliferative disorders or malignant lesions. The histologic and immunohistochemical studies confirmed the diagnosis of LCA and sigmoid volvulus. The post-operative period was uneventful with a significant increase in haemoglobin and platelet levels. Unfortunately, the patient died due to sepsis 36 days after surgery. Conclusion: This is the first case of LCA and sigmoid volvulus. Although this association is likely to be entirely coincidental, clinicians should be aware of this rare clinicopathologic entity whilst evaluating the differential diagnosis of splenomegaly with solitary or multiple nodules.

Keywords: Littoral cell angioma, spleen, vascular tumour, cerebral palsy, sigmoid volvulus, case report, green

Pubmed Style

Salim Gumus, Burak Uz, Faruk Saltabas. Littoral cell angioma of the spleen in a patient with cerebral palsy and sigmoid volvulus: a rare case report. EJMCR. 2020; 25 (February 2020): 60-64. doi:10.24911/ejmcr/173-1559125473

Web Style

Salim Gumus, Burak Uz, Faruk Saltabas. Littoral cell angioma of the spleen in a patient with cerebral palsy and sigmoid volvulus: a rare case report. https://ejmcr.com/articles/1454 [Access: December 25, 2024]. doi:10.24911/ejmcr/173-1559125473

AMA (American Medical Association) Style

Vancouver/ICMJE Style

Salim Gumus, Burak Uz, Faruk Saltabas. Littoral cell angioma of the spleen in a patient with cerebral palsy and sigmoid volvulus: a rare case report. EJMCR. (2020), [cited December 25, 2024]; 25 (February 2020): 60-64. doi:10.24911/ejmcr/173-1559125473

Harvard Style

Salim Gumus, Burak Uz, Faruk Saltabas (2020) Littoral cell angioma of the spleen in a patient with cerebral palsy and sigmoid volvulus: a rare case report. EJMCR, 25 (February 2020): 60-64. doi:10.24911/ejmcr/173-1559125473

Chicago Style

Salim Gumus, Burak Uz, Faruk Saltabas. "Littoral cell angioma of the spleen in a patient with cerebral palsy and sigmoid volvulus: a rare case report." 25 (2020), 60-64. doi:10.24911/ejmcr/173-1559125473

MLA (The Modern Language Association) Style

Salim Gumus, Burak Uz, Faruk Saltabas. "Littoral cell angioma of the spleen in a patient with cerebral palsy and sigmoid volvulus: a rare case report." 25.February 2020 (2020), 60-64. Print. doi:10.24911/ejmcr/173-1559125473

APA (American Psychological Association) Style

Salim Gumus, Burak Uz, Faruk Saltabas (2020) Littoral cell angioma of the spleen in a patient with cerebral palsy and sigmoid volvulus: a rare case report. , 25 (February 2020), 60-64. doi:10.24911/ejmcr/173-1559125473