Case Report
Volume: 4 | Issue: 2 | Published: Feb 25, 2020 | Pages: 60 - 64 | DOI: 10.24911/ejmcr/173-1559125473
Littoral cell angioma of the spleen in a patient with cerebral palsy and sigmoid volvulus: a rare case report
Authors: Salim Gumus , Burak Uz , Faruk Saltabas
Article Info
Authors
Salim Gumus
Department of General Surgery, Medicana International Samsun Hospital, Samsun, Turkey
Burak Uz
Burak Uz, Department of Hematology, Medicana International Samsun Hospital, Samsun, Turkey
Faruk Saltabas
Faruk Saltabas, Department of Pathology, Medicana International Samsun Hospital, Samsun, Turkey
Publication History
Received: June 01, 2019
Revised: December 06, 2019
Accepted: February 17, 2020
Published: February 25, 2020
Abstract
Background: Littoral cell angioma (LCA) is a rare vascular tumour of the spleen with unique histologic and immunophenotypic features. LCA is generally diagnosed incidentally and has a benign clinical course. However, it has rarely been reported to behave as a malign entity. Case presentation: A 49-year-old woman with cerebral palsy admitted to the hospital suffering from abdominal pain and weight loss. Laboratory results revealed iron deficiency anaemia and mild thrombocytopenia. Computed tomography scan revealed splenomegaly with multiple hypoattenuating lesions. A diagnostic and therapeutic open splenectomy and sigmoid colectomy were performed to exclude possible lymphoproliferative disorders or malignant lesions. The histologic and immunohistochemical studies confirmed the diagnosis of LCA and sigmoid volvulus. The post-operative period was uneventful with a significant increase in haemoglobin and platelet levels. Unfortunately, the patient died due to sepsis 36 days after surgery. Conclusion: This is the first case of LCA and sigmoid volvulus. Although this association is likely to be entirely coincidental, clinicians should be aware of this rare clinicopathologic entity whilst evaluating the differential diagnosis of splenomegaly with solitary or multiple nodules.
Keywords: Littoral cell angioma, spleen, vascular tumour, cerebral palsy, sigmoid volvulus, case report, green
Pubmed Style
Salim Gumus, Burak Uz, Faruk Saltabas. Littoral cell angioma of the spleen in a patient with cerebral palsy and sigmoid volvulus: a rare case report. EJMCR. 2020; 25 (February 2020): 60-64. doi:10.24911/ejmcr/173-1559125473
Web Style
Salim Gumus, Burak Uz, Faruk Saltabas. Littoral cell angioma of the spleen in a patient with cerebral palsy and sigmoid volvulus: a rare case report. https://ejmcr.com/articles/1454 [Access: November 23, 2024]. doi:10.24911/ejmcr/173-1559125473
AMA (American Medical Association) Style
Salim Gumus, Burak Uz, Faruk Saltabas. Littoral cell angioma of the spleen in a patient with cerebral palsy and sigmoid volvulus: a rare case report. EJMCR. 2020; 25 (February 2020): 60-64. doi:10.24911/ejmcr/173-1559125473
Vancouver/ICMJE Style
Salim Gumus, Burak Uz, Faruk Saltabas. Littoral cell angioma of the spleen in a patient with cerebral palsy and sigmoid volvulus: a rare case report. EJMCR. (2020), [cited November 23, 2024]; 25 (February 2020): 60-64. doi:10.24911/ejmcr/173-1559125473
Harvard Style
Salim Gumus, Burak Uz, Faruk Saltabas (2020) Littoral cell angioma of the spleen in a patient with cerebral palsy and sigmoid volvulus: a rare case report. EJMCR, 25 (February 2020): 60-64. doi:10.24911/ejmcr/173-1559125473
Chicago Style
Salim Gumus, Burak Uz, Faruk Saltabas. "Littoral cell angioma of the spleen in a patient with cerebral palsy and sigmoid volvulus: a rare case report." 25 (2020), 60-64. doi:10.24911/ejmcr/173-1559125473
MLA (The Modern Language Association) Style
Salim Gumus, Burak Uz, Faruk Saltabas. "Littoral cell angioma of the spleen in a patient with cerebral palsy and sigmoid volvulus: a rare case report." 25.February 2020 (2020), 60-64. Print. doi:10.24911/ejmcr/173-1559125473
APA (American Psychological Association) Style
Salim Gumus, Burak Uz, Faruk Saltabas (2020) Littoral cell angioma of the spleen in a patient with cerebral palsy and sigmoid volvulus: a rare case report. , 25 (February 2020), 60-64. doi:10.24911/ejmcr/173-1559125473